High-grade osteosarcoma arising in DCIA flap reconstruction after a prior resection of maxillar cemento-ossifying fibroma: A case report

• Published in: Journal of stomatology, oral and maxillofacial surgery oral and maxillofacial surgery, 2024-02, Vol.125 (1), p.101591, Article 101591
• Main Authors: Muylaert, Frances, De Kock, Lisa, Creytens, David, Verstraete, Koenraad, Coopman, Renaat
• Format: Article
• Language: English
• ISSN: 2468-7855; 2468-7855
• DOI: 10.1016/j.jormas.2023.101591

Cemento-ossifying fibroma is a rare benign odontogenic tumour of the tooth-bearing jaws. Its concomitant occurrence with osteosarcoma, a malignant maxillofacial bone tumour, has never been described before. We present an uncommon case of a 43-year-old woman in whom a cemento-ossifying fibroma in the right maxilla was treated by resection and reconstruction using a deep circumflex iliac artery flap. During surgical prosthetic rehabilitation one-year post-operative, an osteosarcoma extending from the contralateral maxilla was coincidentally discovered in the deep circumflex iliac artery flap. The aim of this case report is to raise awareness on the extremely rare but possible simultaneous and independent occurrence of a cemento-ossifying fibroma and an osteosarcoma.