Upper limb function in Duchenne muscular dystrophy: 24 month longitudinal data

The aim of the study was to establish 24 month changes in upper limb function using a revised version of the performance of upper limb test (PUL 2.0) in a large cohort of ambulant and non-ambulant boys with Duchenne muscular dystrophy and to identify possible trajectories of progression. Of the 187...

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Bibliographic Details
Published in:PloS one 2018-06, Vol.13 (6), p.e0199223-e0199223
Main Authors: Pane, Marika, Coratti, Giorgia, Brogna, Claudia, Mazzone, Elena Stacy, Mayhew, Anna, Fanelli, Lavinia, Messina, Sonia, D'Amico, Adele, Catteruccia, Michela, Scutifero, Marianna, Frosini, Silvia, Lanzillotta, Valentina, Colia, Giulia, Cavallaro, Filippo, Rolle, Enrica, De Sanctis, Roberto, Forcina, Nicola, Petillo, Roberta, Barp, Andrea, Gardani, Alice, Pini, Antonella, Monaco, Giulia, D'Angelo, Maria Grazia, Zanin, Riccardo, Vita, Gian Luca, Bruno, Claudio, Mongini, Tiziana, Ricci, Federica, Pegoraro, Elena, Bello, Luca, Berardinelli, Angela, Battini, Roberta, Sansone, Valeria, Albamonte, Emilio, Baranello, Giovanni, Bertini, Enrico, Politano, Luisa, Sormani, Maria Pia, Mercuri, Eugenio
Format: Article
Language:English
Subjects:
Adolescent
Arm
Biology and Life Sciences
Child
Child development
Children & youth
Clinical trials
Computer and Information Sciences
Disease Progression
Duchenne muscular dystrophy
Duchenne's muscular dystrophy
Dystrophy
Genetics
Health aspects
Humans
Longitudinal Studies
Male
Medical research
Medicine
Medicine and Health Sciences
Monitoring, Ambulatory
Muscular dystrophy
Muscular Dystrophy, Duchenne - physiopathology
Neurology
Neurosciences
Patients
Pediatrics
Physical Sciences
Physiological aspects
Research and Analysis Methods
Social Sciences
Studies
Supervision
Upper Extremity - physiopathology
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Summary:The aim of the study was to establish 24 month changes in upper limb function using a revised version of the performance of upper limb test (PUL 2.0) in a large cohort of ambulant and non-ambulant boys with Duchenne muscular dystrophy and to identify possible trajectories of progression. Of the 187 patients studied, 87 were ambulant (age range: 7-15.8 years), and 90 non-ambulant (age range: 9.08-24.78). The total scores changed significantly over time (p
ISSN:1932-6203
1932-6203
DOI:10.1371/journal.pone.0199223