A case of uterine lymphangioleiomyomatosis in a young woman that was identified via peritonitis

Although lymphangioleiomyomatosis is often observed with tuberous sclerosis, uterine lymphangioleiomyomatosis is rare. Our patient was 36 years old (gravida 0, para 0). She had a history of tuberous sclerosis, and many myometrial cystic lesions were identified during assisted reproductive therapy. A...

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Bibliographic Details
Published in:The journal of obstetrics and gynaecology research 2019-02, Vol.45 (2), p.482-486
Main Authors: Yoshizawa, Hikari, Kawai, Satoshi, Hirota, Yutaka, Ueda, Takahiro, Kuroda, Makoto, Fujii, Takuma
Format: Article
Language:English
Subjects:
abscess
Adult
Biopsy
Female
Gonadotropins
Humans
Hysterectomy
Lymph nodes
lymphangioleiomyomatosis
Lymphangioleiomyomatosis - diagnosis
Lymphangioleiomyomatosis - etiology
Lymphangioleiomyomatosis - surgery
Myometrium
Myometrium - pathology
Myometrium - surgery
Ovariectomy
Peritonitis
Peritonitis - diagnosis
Peritonitis - etiology
Peritonitis - surgery
Pituitary (anterior)
Reproduction
Salpingo-oophorectomy
Tuberous sclerosis
Tuberous Sclerosis - complications
tuberous sclerosis complex
Uterine Diseases - diagnosis
Uterine Diseases - etiology
Uterine Diseases - surgery
Uterus
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Summary:Although lymphangioleiomyomatosis is often observed with tuberous sclerosis, uterine lymphangioleiomyomatosis is rare. Our patient was 36 years old (gravida 0, para 0). She had a history of tuberous sclerosis, and many myometrial cystic lesions were identified during assisted reproductive therapy. Although we administered a gonadotropin‐releasing hormone analog, myometrial cystic lesions increased in size. Therefore, simple hysterectomy, bilateral salpingo‐oophorectomy and pelvic lymph node biopsy were performed. Postoperative histology showed lymphangioleiomyomatosis and myometrial abscess. For uterine lesions in young women with tuberous sclerosis, the possibility of uterine lymphangioleiomyomatosis should also be considered.
ISSN:1341-8076
1447-0756
DOI:10.1111/jog.13822