Congenital oral synechia and ankyloblepharon filiforme adnatum: Case report and literature review

Abstract Introduction Congenital intraoral synechias are adhesions of intraoral structures involving soft tissue. These conditions and another anomaly called ankyloblepharon filiforme adnatum, which is partial fusion of the eyelid margins by bands of tissue, are rarely reported in the literature. Th...

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Published in:International journal of pediatric otorhinolaryngology 2016-11, Vol.90, p.196-199
Main Authors: Lima, Lívia Bonjardim, DDS, Barbosa de Paulo, Luiz Fernando, DDS, MSC, PhD, Silva, Cláudia Jordão, DDS, MSC, PhD, Mendes, Vanessa Cristina, DDS, MSC, PhD, Simamoto-Júnior, Paulo Cézar, DDS, MSC, PhD, Durighetto, Antônio Francisco, DDS, MSC, PhD
Format: Article
Language:English
Subjects:
Ankyloblepharon filiforme adnatum
Cleft Lip - complications
Cleft Lip - diagnosis
Cleft Lip - surgery
Cleft Palate - complications
Cleft Palate - diagnosis
Cleft Palate - surgery
Congenital defects
Ectopic tissue
Eye Abnormalities - complications
Eye Abnormalities - diagnosis
Eye Abnormalities - surgery
Female
Humans
Infant, Newborn
Jaw abnormality
Mouth Abnormalities - complications
Mouth Abnormalities - diagnosis
Mouth Abnormalities - surgery
Mouth Mucosa
Otolaryngology
Pediatrics
Tissue Adhesions - diagnosis
Tissue Adhesions - surgery
Tongue
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Summary:Abstract Introduction Congenital intraoral synechias are adhesions of intraoral structures involving soft tissue. These conditions and another anomaly called ankyloblepharon filiforme adnatum, which is partial fusion of the eyelid margins by bands of tissue, are rarely reported in the literature. The association of both anomalies of the craniomaxillofacial region is an even more unusual finding. Purpose This article adds more information to the literature by reporting a case of a neonate with a rare association of bilateral synechia between the jaws, fusion of buccal mucosa to the ridges and between the tongue and palate, and ankyloblepharon filiforme adnatum in both eyes, without any other facial or systemic malformation. Methods A literature review of similar cases published in PUBMED/MEDLINE was conducted followed by a discussion and comparison to the new case. Conclusion The rare association of these congenital defects, without the presence of syndromic symptoms, could be diagnosed and treated easily with good prognostic evolution.
ISSN:0165-5876
1872-8464
DOI:10.1016/j.ijporl.2016.09.023