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Two cases of aplasia cutis congenita with hair collar signs and macrophage hyperplasia

We report two cases of aplasia cutis congenita associated with hair collar signs and hemangioma simplex in their parietal regions. A hair collar sign and a hemangioma are known to suggest the possibility of underlying neural tube defects. However, no obvious bone defects or heterotopic neural tissue...

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Published in:	Journal of dermatology 2019-08, Vol.46 (8), p.734-738
Main Authors:	Takayama, Eriko, Harada, Atsuko, Ikura, Yoshihiro, Seto, Hidenobu
Format:	Article
Language:	English
Subjects:	Aplasia aplasia cutis congenita Appendages Bone imaging Collagen dermal melanocytosis ectodermal fusion Epidermis Fibers Follicles Hair hair collar sign Hemangioma Hyperplasia Macrophages Melanocytes Neural tube defects Skin
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description	We report two cases of aplasia cutis congenita associated with hair collar signs and hemangioma simplex in their parietal regions. A hair collar sign and a hemangioma are known to suggest the possibility of underlying neural tube defects. However, no obvious bone defects or heterotopic neural tissue were observed in the imaging and histopathological examinations. Nevertheless, some pathological observations similar in both cases suggested abnormalities in the process of ectodermal fusion. A flat epidermis and a lack of appendages were recognized. Both cases also exhibited the presence of melanocytes in a portion of the superficial dermal layer. An increase in the number of macrophages was observed in the dermal area with neither elastic fibers nor normal collagen fibers. The peripheral hair follicles grew horizontally.
doi_str_mv	10.1111/1346-8138.14946
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source	Wiley-Blackwell Read & Publish Collection
subjects	Aplasia aplasia cutis congenita Appendages Bone imaging Collagen dermal melanocytosis ectodermal fusion Epidermis Fibers Follicles Hair hair collar sign Hemangioma Hyperplasia Macrophages Melanocytes Neural tube defects Skin
title	Two cases of aplasia cutis congenita with hair collar signs and macrophage hyperplasia
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