Atypical and typical cranial dystonia following dental procedures

• Published in: Movement disorders 1999-05, Vol.14 (3), p.492-496
• Main Authors: Schrag, Anette, Bhatia, Kailash P., Quinn, Niall P., Marsden, C. David
• Format: Article
• Language: English
• Subjects: Adult; Atypical; Biological and medical sciences; Cranial dystonia; Dental; Diseases of striated muscles. Neuromuscular diseases; Dystonia - diagnosis; Dystonia - etiology; Dystonia - physiopathology; Ent and stomatology; Facial Muscles - physiopathology; Female; Humans; Male; Medical sciences; Middle Aged; Muscular Diseases - physiopathology; Neurology; Oral Surgical Procedures - adverse effects; Pain; Peripheral; Radiotherapy. Instrumental treatment. Physiotherapy. Reeducation. Rehabilitation, orthophony, crenotherapy. Diet therapy and various other treatments (general aspects); Severity of Illness Index; Spasm - physiopathology; Stomatology; Time Factors; Trauma
• ISSN: 0885-3185; 1531-8257
• DOI: 10.1002/1531-8257(199905)14:3<492::AID-MDS1018>3.0.CO;2-4

It is generally recognized that focal dystonia of the limbs or cervical region and blepharospasm sometimes follow, and in these cases may be caused or triggered by, peripheral injury. However, the association between peripheral injury and lower cranial dystonia is rare. We report eight cases who developed cranial dystonia within hours to months following a dental procedure. One group of five cases, all women, developed atypical dystonia associated with painful paresthesias at the site of dystonia. Two of these five cases had fixed jaw‐deviating dystonia, whereas the remaining three had additional tremor and spread of their dystonia to involve the tongue in all three, and the lips and neck in two cases. These five patients are reminiscent of cases of limb causalgia–dystonia syndrome, which occurs after minor peripheral trauma and can spread. The remaining three cases developed more typical cranial dystonia following the dental procedure. There was no family history of dystonia or prior use of neuroleptics in any of the patients. The close association in time and location of the procedure and onset of symptoms suggests that the onset of the dystonia may have been caused by the dental intervention, but whether there is a causal relationship between the dental intervention and the development of the dyskinesias requires further epidemiologic studies.