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case of Hughes-Stovin syndrome associated with hyperhomocysteinemia
We report a case of Hughes-Stovin syndrome (HSS) associated with hyperhomocysteinemia. A 24-year-old man who has no clinical features suggestive of Behcet's disease was admitted for hemoptysis and dyspnea. Radiological and laboratory evaluation revealed multifocal pulmonary artery aneurysms inv...
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| Published in: | Clinical rheumatology 2010-07, Vol.29 (7), p.807-809 |
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| Main Authors: | , , , , , , , |
| Format: | Article |
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| cites | cdi_FETCH-LOGICAL-c394t-f8bc47fe1bd5d0b823d185f1e830213c4bdc24f31c6fb5af01db7dc6d00942393 |
| container_end_page | 809 |
| container_issue | 7 |
| container_start_page | 807 |
| container_title | Clinical rheumatology |
| container_volume | 29 |
| creator | Kim, Hyun-Ok Kim, Ho Cheol Park, Yongwhi Jeong, Yong-Geun Kim, Jae Hee Jeon, Dae-Hong Jeon, Kyoung-Nyeo Lee, Sang-Il |
| description | We report a case of Hughes-Stovin syndrome (HSS) associated with hyperhomocysteinemia. A 24-year-old man who has no clinical features suggestive of Behcet's disease was admitted for hemoptysis and dyspnea. Radiological and laboratory evaluation revealed multifocal pulmonary artery aneurysms involving bilateral segmental pulmonary artery, thrombi in right atrium and ventricle, and hyperhomocysteinemia. Accordingly, HSS associated with hyperhomocysteinemia was diagnosed, and the clinical and radiological improvement was achieved after treatment with prednisolone, warfarin, and folic acid. |
| doi_str_mv | 10.1007/s10067-010-1393-7 |
| format | article |
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A 24-year-old man who has no clinical features suggestive of Behcet's disease was admitted for hemoptysis and dyspnea. Radiological and laboratory evaluation revealed multifocal pulmonary artery aneurysms involving bilateral segmental pulmonary artery, thrombi in right atrium and ventricle, and hyperhomocysteinemia. Accordingly, HSS associated with hyperhomocysteinemia was diagnosed, and the clinical and radiological improvement was achieved after treatment with prednisolone, warfarin, and folic acid.</description><identifier>ISSN: 0770-3198</identifier><identifier>EISSN: 1434-9949</identifier><identifier>DOI: 10.1007/s10067-010-1393-7</identifier><identifier>PMID: 20140757</identifier><language>eng</language><publisher>London: London : Springer-Verlag</publisher><subject>aneurysm ; Anti-Inflammatory Agents - therapeutic use ; Anticoagulants - therapeutic use ; Behcet's disease ; Case Report ; Dyspnea - complications ; Dyspnea - drug therapy ; Folic Acid - therapeutic use ; Hematinics - therapeutic use ; Hemoptysis - complications ; Hemoptysis - drug therapy ; Hughes-Stovin syndrome ; Humans ; Hyperhomocysteinemia ; Hyperhomocysteinemia - complications ; Hyperhomocysteinemia - drug therapy ; Male ; Medicine ; Medicine & Public Health ; Prednisolone - therapeutic use ; Rheumatology ; Syndrome ; Treatment Outcome ; Warfarin - therapeutic use ; Young Adult</subject><ispartof>Clinical rheumatology, 2010-07, Vol.29 (7), p.807-809</ispartof><rights>Clinical Rheumatology 2010</rights><lds50>peer_reviewed</lds50><woscitedreferencessubscribed>false</woscitedreferencessubscribed><citedby>FETCH-LOGICAL-c394t-f8bc47fe1bd5d0b823d185f1e830213c4bdc24f31c6fb5af01db7dc6d00942393</citedby><cites>FETCH-LOGICAL-c394t-f8bc47fe1bd5d0b823d185f1e830213c4bdc24f31c6fb5af01db7dc6d00942393</cites></display><links><openurl>$$Topenurl_article</openurl><openurlfulltext>$$Topenurlfull_article</openurlfulltext><thumbnail>$$Tsyndetics_thumb_exl</thumbnail><link.rule.ids>314,780,784,27923,27924</link.rule.ids><backlink>$$Uhttps://www.ncbi.nlm.nih.gov/pubmed/20140757$$D View this record in MEDLINE/PubMed$$Hfree_for_read</backlink></links><search><creatorcontrib>Kim, Hyun-Ok</creatorcontrib><creatorcontrib>Kim, Ho Cheol</creatorcontrib><creatorcontrib>Park, Yongwhi</creatorcontrib><creatorcontrib>Jeong, Yong-Geun</creatorcontrib><creatorcontrib>Kim, Jae Hee</creatorcontrib><creatorcontrib>Jeon, Dae-Hong</creatorcontrib><creatorcontrib>Jeon, Kyoung-Nyeo</creatorcontrib><creatorcontrib>Lee, Sang-Il</creatorcontrib><title>case of Hughes-Stovin syndrome associated with hyperhomocysteinemia</title><title>Clinical rheumatology</title><addtitle>Clin Rheumatol</addtitle><addtitle>Clin Rheumatol</addtitle><description>We report a case of Hughes-Stovin syndrome (HSS) associated with hyperhomocysteinemia. A 24-year-old man who has no clinical features suggestive of Behcet's disease was admitted for hemoptysis and dyspnea. Radiological and laboratory evaluation revealed multifocal pulmonary artery aneurysms involving bilateral segmental pulmonary artery, thrombi in right atrium and ventricle, and hyperhomocysteinemia. 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A 24-year-old man who has no clinical features suggestive of Behcet's disease was admitted for hemoptysis and dyspnea. Radiological and laboratory evaluation revealed multifocal pulmonary artery aneurysms involving bilateral segmental pulmonary artery, thrombi in right atrium and ventricle, and hyperhomocysteinemia. Accordingly, HSS associated with hyperhomocysteinemia was diagnosed, and the clinical and radiological improvement was achieved after treatment with prednisolone, warfarin, and folic acid.</abstract><cop>London</cop><pub>London : Springer-Verlag</pub><pmid>20140757</pmid><doi>10.1007/s10067-010-1393-7</doi><tpages>3</tpages></addata></record> |
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| ispartof | Clinical rheumatology, 2010-07, Vol.29 (7), p.807-809 |
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| source | Springer Nature:Jisc Collections:Springer Nature Read and Publish 2023-2025: Springer Reading List |
| subjects | aneurysm Anti-Inflammatory Agents - therapeutic use Anticoagulants - therapeutic use Behcet's disease Case Report Dyspnea - complications Dyspnea - drug therapy Folic Acid - therapeutic use Hematinics - therapeutic use Hemoptysis - complications Hemoptysis - drug therapy Hughes-Stovin syndrome Humans Hyperhomocysteinemia Hyperhomocysteinemia - complications Hyperhomocysteinemia - drug therapy Male Medicine Medicine & Public Health Prednisolone - therapeutic use Rheumatology Syndrome Treatment Outcome Warfarin - therapeutic use Young Adult |
| title | case of Hughes-Stovin syndrome associated with hyperhomocysteinemia |
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