Long-Term Follow-Up of Bimaxillary Osteomyelitis Associated with Autosomal Dominant Osteopetrosis: A Case Report

Osteopetrosis (OP) is a rare metabolic bone disease characterized by a generalized increase in skeletal mass. The disease is characterized by increased susceptibility to develop osteomyelitis of the jaws. We report a case of clinical and radiological progression of bimaxillary osteomyelitis in a pat...

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Bibliographic Details
Published in:Journal of maxillofacial and oral surgery 2016-03, Vol.15 (1), p.121-126
Main Authors: Kulyapina, A., Verdaguer Martin, J., Navarro Cuellar, C., Navarro Vila, C.
Format: Article
Language:English
Subjects:
Abscesses
Anemia
Antibiotics
Bone density
Bones
Case Report
Case reports
Dentistry
Fistula
Fractures
General anesthesia
Jaw
Medical imaging
Medicine
Medicine & Public Health
Oral and Maxillofacial Surgery
Otorhinolaryngology
Pathology
Plastic Surgery
Radiography
Teeth
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Summary:Osteopetrosis (OP) is a rare metabolic bone disease characterized by a generalized increase in skeletal mass. The disease is characterized by increased susceptibility to develop osteomyelitis of the jaws. We report a case of clinical and radiological progression of bimaxillary osteomyelitis in a patient with autosomal dominant OP. The patient presented non simultaneous osteomyelitis in both upper and lower jaws with time interval of 10 years. The osteomyelitis of maxilla resulted in oroantral fistula formation and required surgical closure with Bichat fat pad flap. The mandibular osteomyelitis resulted in sequestra formation and pathological fracture and required multiple debridement procedures. Both maxillary and mandibular osteomyelitic foci were persistent and healing required more than 2 years. The case confirms the possibility of development of non simultaneous bimaxillary osteomyelitis in patients with OP. The case enhances the need of close follow- up and preventive measures in patients with OP.
ISSN:0972-8279
0974-942X
DOI:10.1007/s12663-015-0749-6