A rare case of recurrent congenital sialolipoma of parotid gland in a 3‑year‑old child: A case report and review of literature

• Published in: International journal of surgery case reports 2021-04, Vol.81, p.105784, Article 105784
• Main Authors: Salama, Khadija, Lahjaouj, M., Merzouqi, B., Oukessou, Youssef, Rouadi, Sami, Abada, Reda, Roubal, Mohamed, Mahtar, Mohamed, Jamaa, Dounia, Karkouri, Mehdi
• Format: Article
• Language: English
• Subjects: Case Report; Child; Congenital; Parotid; Recurrence; Sialolipoma
• ISSN: 2210-2612; 2210-2612
• DOI: 10.1016/j.ijscr.2021.105784

•Sialolipoma is a rare salivary gland tumor defined histologically by mature adipocytes encasing normal salivary glandular components.•Complete excision of the mass with the lobes of the salivary glands involved seems to be adequate for definitive management.•Congenital sialolipoma should be kept in mind in the differential diagnosis of congenital parotid mass, especially when CT scanning shows a well‑circumscribed fat‑like tissue within the parotid gland.•Although surgical excision is usually sufficient to treat sialolipoma of the parotid gland, postoperative follow-up is necessary as multifocal lesions can potentially persist, which could lead to recurrence. Sialolipoma is an extremely rare salivary gland tumor characterized by a well circumscribed mass composed of glandular tissue and matures adipose elements. Herein,the aim of this article is to report the sixth case of congenital sialolipoma and the first case of recurrent congenital sialolipoma in infant, and discuss the clinicopathological and morphological features of sialolipoma and the possible cause of its recurrence. A 3 year-old child presented with a recurrent mass of right parotid gland which progressed from birth, initially treated at the age of 4 months by simple tumorectomy and excision of the surrounding parotid tissue. The tumor recurred 4 months postoperatively. The radiological examination confirmed the parotid origin of the tumor. Histopathology was consistent with a sialolipoma. A superficial parotidectomy with preservation of the facial nerve was performed this time at the age of 3 years. Postoperative recovery proceeded without incident with normal facial nerve function. There was no recurrence at 36-month follow-up. Although it is a very rare benign tumor, congenital sialolipoma should be kept in mind in the differential diagnosis of congenital parotid mass. The recurrence of congenital sialolipoma is dependent on its management, thus complete excision of the mass with the lobes of the salivary glands involved seems to be adequate for definitive management.